Compression of the Diseased Segment and Regeneration through Healthy Bone for Salvage of Infected Recurrent Congenital Pseudarthrosis of the Tibia in an Adult: A Case Report
Year: 2026
Type: article
Abstract: Introduction: Congenital pseudarthrosis of the tibia (CPT) is a rare dysplastic disorder characterized by persistent non-union and recurrent fracture. Management becomes particularly challenging in multiply operated adults with limb-length discrepancy (LLD), deformity, and compromised local biology. Deep infection involving a previously reconstructed CPT segment further limits conventional fixation options. Case Report: An 18-year-old male with recurrent CPT and multiple previous surgical procedures presented with an unstable tibial pseudarthrosis, 5-cm LLD, and ankle valgus. Initial Ilizarov compression failed to achieve union. Subsequent excision of the pseudarthrosis and tricortical iliac crest grafting achieved initial union but was complicated by graft-site fracture and deep Staphylococcus aureus infection. Following radical debridement, a multilevel Ilizarov construct was used to achieve acute compression at the infected pseudarthrosis and proximal tibial distraction osteogenesis in healthy bone. Union, infection eradication, and limb-length restoration were achieved and maintained at 24-month follow-up. Conclusion: Simultaneous compression of an infected CPT site and distraction osteogenesis through healthy bone may provide a limb-salvage strategy in complex adult CPT when internal fixation is unsuitable.
Language: English
Subfield: Orthopedics and Sports Medicine
Field: Medicine
Domain: Health Sciences
Open Access status: gold
Estimated APC paid: $250
OpenAlex ID: W7225597774
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